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Laryngotracheal reconstruction for relapsing polychondritis: case report and review of the literature

Published online by Cambridge University Press:  07 August 2013

C Xie ,
N Shah ,
P L Shah  and
G Sandhu
C Xie*
Affiliation:
ENT Department, Charing Cross Hospital, Imperial College Trust, London, UK
N Shah
Affiliation:
University College London Medical School, University College London, UK
P L Shah
Affiliation:
Respiratory Medicine Department, Royal Brompton and Harefield NHS Foundation Trust, London, UK Respiratory Medicine Department, Chelsea and Westminster Hospital, London, UK
G Sandhu
Affiliation:
ENT Department, Charing Cross Hospital, Imperial College Trust, London, UK
*
Address for correspondence: Ms C Xie, Flat 24, College House, 52 Putney Hill, London SW15 6BF, UK E-mail: carolx@doctors.net.uk
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Abstract

Background:

Relapsing polychondritis is a multi-system autoimmune disease characterised by the inflammation and destruction of cartilaginous structures. The most common sites are the pinna, nose, laryngotracheobronchial tree and peripheral joints. Airway involvement occurs in up to half of patients affected, at any disease stage. It is the most severe and life-threatening aspect of the disease, and proves to be a therapeutic challenge.

Objectives:

This article reports our experience of performing laryngotracheal reconstruction in a patient with relapsing polychondritis. A review of the literature is presented, with a focused discussion of airway treatment options.

Methods:

Laryngotracheal reconstruction for relapsing polychondritis was performed using hyoid bone pedicled on sternohyoid muscle.

Conclusion:

Airway management in relapsing polychondritis can improve quality of life and palliate patients effectively.

Keywords

LarynxTracheaPolychondritisRelapsingOtorhinolaryngological Surgical ProceduresDiagnosis
Type
Short Communications
Information
The Journal of Laryngology & Otology , Volume 127 , Issue 9 , September 2013 , pp. 932 - 935
Copyright
Copyright © JLO (1984) Limited 2013 

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