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Loeffler’s group 2 cor triatriatum sinistrum with mobile left atrial thrombus – a case report and literature review

Published online by Cambridge University Press:  16 December 2020

Yuan Zheng ,
Wei Zhu ,
Xinjie Huang  and
Dongqun Lin Open the ORCID record for Dongqun Lin [Opens in a new window]
Yuan Zheng
Affiliation:
Department of cardiothoracic surgery, Guangdong Provincial hospital of Chinese Medicine, No.55 Neihuanxi Road, Panyu, Guangzhou, Guangdong510006, People’s Republic of China
Wei Zhu
Affiliation:
Department of cardiothoracic surgery, Guangdong Provincial hospital of Chinese Medicine, No.55 Neihuanxi Road, Panyu, Guangzhou, Guangdong510006, People’s Republic of China
Xinjie Huang
Affiliation:
Department of cardiothoracic surgery, Guangdong Provincial hospital of Chinese Medicine, No.55 Neihuanxi Road, Panyu, Guangzhou, Guangdong510006, People’s Republic of China
Dongqun Lin*
Affiliation:
Department of cardiothoracic surgery, Guangdong Provincial hospital of Chinese Medicine, No.55 Neihuanxi Road, Panyu, Guangzhou, Guangdong510006, People’s Republic of China
*
Author for correspondence: Dongqun Lin MD, Guangdong Provincial Hospital of Chinese Medicine, No.55 Neihuanxi Road, Panyu, Guangzhou, Guangdong 510006, People’s Republic of China. Tel: +020-39318581. Fax: +020-34728881. E-mail: dongqunlin123@gmail.com
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Abstract

We report a case of a 25-year-old man diagnosed with an unusual case of cor triatriatum sinister with a mobile left atrial thrombus. He was hospitalised with aggravating dyspnoea. Transthoracic echocardiography revealed a membrane-like structure traversing the left atrial and a small orifice of about 7.1 mm. The mean pressure gradient was 12.94 mmHg across the orifice of the membrane-like structure and there was a mobile mass in the post-erosuperior chamber. The anomaly was rectified by a surgical resection. Timely diagnosis and surgical repair may prevent stroke in patients with unusual cor triatriatum sinister.

Keywords

Cor triatriatum sinistercase reportmobile thrombustransthoracic echocardiography
Type
Brief Report
Information
Cardiology in the Young , Volume 31 , Issue 4 , April 2021 , pp. 666 - 668
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Copyright
© The Author(s), 2020. Published by Cambridge University Press

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References

Nassar, PN, Hamdan, RH. Cor triatriatum sinistrum: classification and imaging modalities. Eur J Cardiovasc Med 2011; 1 (3): 84–87. doi: 10.5083/ejcm.20424884.21.CrossRefGoogle ScholarPubMed
Gheissari, A, Malm, JR, Bowman, FO, Bierman, FZ. Cor triatriatum sinistrum: one institution’s 28-year experience. Pediatr Cardiol 1992; 13 (2): 85–88. doi: 10.1007/BF00798210.CrossRefGoogle ScholarPubMed
Hayes, C, Liu, S, Tam, JW, Kass, M. Cor triatriatum sinister: an unusual cause of atrial fibrillation in adults. Case Rep Cardiol 2018; 2018: 1–3. doi: 10.1155/2018/9242519.CrossRefGoogle ScholarPubMed
Chennadi, S, Zulqarnain, S. A rare case of subtotal cor triatriatum sinistrum. Chest 2015; 148 (4): 976A. doi: 10.1378/chest.2273577.CrossRefGoogle Scholar
Rozema, TK, Arruda, J, Snyder, CS. Cor triatriatum: a tale of two membranes. CASE (Phila) 2019; 3 (1): 25–27. doi: 10.1016/j.case.2018.08.003.Google ScholarPubMed
Rudienė, V, Hjortshøj, CMS, Glaveckaitė, S, et al. Cor triatriatum sinistrum diagnosed in the adulthood: a systematic review. Heart 2019; 105 (15): 1197–1202. doi: 10.1136/heartjnl-2019-314714.Google ScholarPubMed
Kokotsakis, J, Anagnostakou, V, Almpanis, G, et al. Cor triatriatum presenting as heart failure with reduced ejection fraction: a case report. J Cardiothorac Surg 2011; 6 (1): 83. doi: 10.1186/1749-8090-6-83.CrossRefGoogle ScholarPubMed
Zepeda, IA, Morcos, P, Castellanos, LR. Cor triatriatum sinister identified after new onset atrial fibrillation in an elderly man. Case Rep Med 2014; 2014: 1–5. doi: 10.1155/2014/674018.CrossRefGoogle Scholar
Diestro, JDB, Regaldo, JJH, Gonzales, EM, Dorotan, MKC, Espiritu, AI, Pascual, JLR. Cor triatriatum and stroke. BMJ Case Rep 2017; 2017. doi: 10.1136/bcr-2017-219763.CrossRefGoogle Scholar
Saxena, P, Burkhart, HM, Schaff, HV, Daly, R, Joyce, LD, Dearani, JA. Surgical repair of cor triatriatum sinister: the Mayo clinic 50-year experience. Ann Thorac Surg 2014; 97 (5): 1659–1663. doi: 10.1016/j.athoracsur.2013.12.046.CrossRefGoogle Scholar
Stiermaier, T, Reil, JC, Eitel, I. Cor triatriatum sinister. Clin Res Cardiol 2018; 107 (5): 447–448. doi: 10.1007/s00392-017-1197-8.CrossRefGoogle ScholarPubMed
Jha, AK, Makhija, N. Cor triatriatum: a review. Semin Cardiothorac Vasc Anesth 2017; 21 (2): 178–185. doi: 10.1177/1089253216680495.CrossRefGoogle ScholarPubMed
Baris, L, Bogers, AJJC, van den Bos, EJ, Kofflard, MJM. Adult cor triatriatum sinistrum: a rare cause of ischaemic stroke. Neth Heart J 2017; 25 (3): 217–220. doi: 10.1007/s12471-016-0938-z.CrossRefGoogle ScholarPubMed
Park, K-J, Park, I-K, Sir, J-J, et al. Adult cor triatriatum presenting as cardioembolic stroke. Intern Med 2009; 48 (13): 1149–1152. doi: 10.2169/internalmedicine.48.2148.CrossRefGoogle ScholarPubMed
Shah, P, Mittal, V, Gupta, N, et al. Isolated cor-triatriatum sinister presenting as new onset atrial-fibrillation in a 53-year-old female. Chest 2012; 142 (4): 119A. doi: 10.1378/chest.1388838.CrossRefGoogle Scholar
Troxclair, D, Ross, KF, Newman, WP. Cor triatriatum sinistrum: a rare congenital cardiac anomaly presenting in an adult with chronic atrial fibrillation. Am J Forensic Med Pathol 2005; 26 (3): 282–284. doi: 10.1097/01.paf.0000176278.76218.93.CrossRefGoogle Scholar
Loeffler, E. Unusual malformation of the left atrium; pulmonary sinus. Arch Pathol (Chic) 1949; 48 (5): 371–376.Google ScholarPubMed
Khanra, D, Soni, S, Ola, R, Duggal, B. Cor triatriatum sinister presenting with acute myocardial infarction. J Pract Cardiovasc Sci 2019; 5 (3): 208. doi: 10.4103/jpcs.jpcs_40_19.CrossRefGoogle Scholar
Alphonso, N, Nørgaard, MA, Newcomb, A, d’Udekem, Y, Brizard, CP, Cochrane, A. Cor triatriatum: presentation, diagnosis and long-term surgical results. Ann Thorac Surg 2005; 80 (5): 1666–1671. doi: 10.1016/j.athoracsur.2005.04.055.CrossRefGoogle ScholarPubMed
Ridjab, DA, Wittchen, F, Tschishow, W, et al. Cor triatriatum sinister and cryptogenic stroke. Herz 2015; 40 (3): 447–448. doi: 10.1007/s00059-013-3934-8.CrossRefGoogle ScholarPubMed
Spengos, K, Gialafos, E, Vassilopoulou, S. Ischemic stroke as an uncommon complication of cor triatriatum. J Stroke Cerebrovasc Dis 2008; 17 (6): 436–438. doi: 10.1016/j.jstrokecerebrovasdis.2008.07.007.CrossRefGoogle ScholarPubMed